Total submissions: 8
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000801307 | SCV000941078 | uncertain significance | Familial Mediterranean fever | 2022-07-25 | criteria provided, single submitter | clinical testing | This sequence change replaces alanine, which is neutral and non-polar, with valine, which is neutral and non-polar, at codon 511 of the MEFV protein (p.Ala511Val). This variant is present in population databases (rs144270019, gnomAD 0.01%). This missense change has been observed in individual(s) with familial Mediterranean fever (PMID: 22281876). ClinVar contains an entry for this variant (Variation ID: 646921). Algorithms developed to predict the effect of missense changes on protein structure and function (SIFT, PolyPhen-2, Align-GVGD) all suggest that this variant is likely to be tolerated. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Mendelics | RCV000801307 | SCV001139849 | uncertain significance | Familial Mediterranean fever | 2019-05-28 | criteria provided, single submitter | clinical testing | |
Women's Health and Genetics/Laboratory Corporation of America, |
RCV001193207 | SCV001361913 | uncertain significance | not specified | 2019-08-15 | criteria provided, single submitter | clinical testing | Variant summary: MEFV c.1532C>T (p.Ala511Val) results in a non-conservative amino acid change in the encoded protein sequence. Four of five in-silico tools predict a benign effect of the variant on protein function. The variant allele was found at a frequency of 4e-05 in 251462 control chromosomes (gnomAD). This frequency is not significantly higher than expected for a pathogenic variant in MEFV causing Familial Mediterranean Fever (4e-05 vs 0.022), allowing no conclusion about variant significance. The variant, c.1532C>T, has been reported in the literature in individuals affected with Familial Mediterranean Fever (Akar_2010, Vergara_2012). These reports do not provide unequivocal conclusions about association of the variant with Familial Mediterranean Fever. To our knowledge, no experimental evidence demonstrating an impact on protein function has been reported. No clinical diagnostic laboratories have submitted clinical-significance assessments for this variant to ClinVar after 2014. Based on the evidence outlined above, the variant was classified as uncertain significance. |
Fulgent Genetics, |
RCV002501072 | SCV002776406 | uncertain significance | Familial Mediterranean fever; Familial Mediterranean fever, autosomal dominant; Acute febrile neutrophilic dermatosis | 2022-05-04 | criteria provided, single submitter | clinical testing | |
Genome- |
RCV000801307 | SCV003802094 | likely benign | Familial Mediterranean fever | 2023-02-08 | criteria provided, single submitter | clinical testing | |
Genome- |
RCV003126939 | SCV003802095 | benign | Familial Mediterranean fever, autosomal dominant | 2023-02-08 | criteria provided, single submitter | clinical testing | |
Genome- |
RCV003126940 | SCV003802096 | benign | Acute febrile neutrophilic dermatosis | 2023-02-08 | criteria provided, single submitter | clinical testing | |
Natera, |
RCV000801307 | SCV001452068 | uncertain significance | Familial Mediterranean fever | 2020-09-16 | no assertion criteria provided | clinical testing |