Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Ambry Genetics | RCV000166723 | SCV000217534 | pathogenic | Hereditary cancer-predisposing syndrome | 2014-11-02 | criteria provided, single submitter | clinical testing | The p.L277* pathogenic mutation (also known as c.830T>G), located in coding exon 5 of the MSH2 gene, results from a T to G substitution at nucleotide position 830. This changes the amino acid from a leucine to a stop codon within coding exon 5. This mutation was observed in a male diagnosed with MSI-H colon cancer at age 37, whose family met Bethesda criteria (Hampel, H et al. J Clin Oncol. 2008 Dec 10;26(35):5783-8). In addition to the clinical data presented in the literature, since premature stop codons are typically deleterious in nature, this alteration is interpreted as a disease-causing mutation (ACMG Recommendations for Standards for Interpretation and Reporting of Sequence Variations. Revision 2007. Genet Med. 2008;10:294). |
Labcorp Genetics |
RCV001205245 | SCV001376486 | pathogenic | Hereditary nonpolyposis colorectal neoplasms | 2023-04-15 | criteria provided, single submitter | clinical testing | This sequence change creates a premature translational stop signal (p.Leu277*) in the MSH2 gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in MSH2 are known to be pathogenic (PMID: 15849733, 24362816). This variant is not present in population databases (gnomAD no frequency). This premature translational stop signal has been observed in individual(s) with colorectal cancer (PMID: 18809606, 28514183). ClinVar contains an entry for this variant (Variation ID: 187038). For these reasons, this variant has been classified as Pathogenic. |
Myriad Genetics, |
RCV003454416 | SCV004186919 | pathogenic | Lynch syndrome 1 | 2023-07-28 | criteria provided, single submitter | clinical testing | This variant is considered pathogenic. This variant creates a termination codon and is predicted to result in premature protein truncation. |
Baylor Genetics | RCV003454416 | SCV004194532 | pathogenic | Lynch syndrome 1 | 2023-06-28 | criteria provided, single submitter | clinical testing |