Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV000413681 | SCV000491203 | likely pathogenic | not provided | 2016-05-20 | criteria provided, single submitter | clinical testing | The c.4074delC likely pathogenic variant in the MYO7A gene has been reported previously in association with Usher syndrome type 2 in an individual who also harbored the C419F variant in the USH2A gene (Cremers et al., 2007). The c.4074delC variant causes a frameshift starting with codon Glutamic Acid 1359, changes this amino acid to an Arginine residue, and creates a premature Stop codon at position 40 of the new reading frame, denoted p.Glu1359ArgfsX40. This variant is predicted to cause loss of normal protein function either through protein truncation or nonsense-mediated mRNA decay. The variant was not observed in approximately 6400 individuals of European and African American ancestry in the NHLBI Exome Sequencing Project, indicating it is not a common benign variant in these populations. We interpret c.4074delC as a likely pathogenic variant. |