Total submissions: 5
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV000418772 | SCV000516815 | pathogenic | not provided | 2015-04-22 | criteria provided, single submitter | clinical testing | The C128X nonsense variant in the NDP gene has been reported previously in association with Norriedisease (Wong et al., 1993; Schuback et al., 1995). This variant is predicted to cause loss of normal protein function through protein truncation. Therefore, we interpret this variant as pathogenic. |
Eurofins Ntd Llc |
RCV000418772 | SCV000700538 | pathogenic | not provided | 2016-10-10 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV000418772 | SCV002238050 | pathogenic | not provided | 2021-07-07 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Pathogenic. This variant disrupts a region of the NDP protein in which other variant(s) (p.Cys131*) have been determined to be pathogenic (PMID: 25711638; Invitae). This suggests that this is a clinically significant region of the protein, and that variants that disrupt it are likely to be disease-causing. ClinVar contains an entry for this variant (Variation ID: 10686). This variant is also known as C792A (Cys128stp). This premature translational stop signal has been observed in individuals with Norrie disease (PMID: 7627181, 8240113). This variant is not present in population databases (ExAC no frequency). This sequence change creates a premature translational stop signal (p.Cys128*) in the NDP gene. While this is not anticipated to result in nonsense mediated decay, it is expected to disrupt the last 6 amino acid(s) of the NDP protein. |
Molecular Medicine, |
RCV000011432 | SCV004023262 | pathogenic | Atrophia bulborum hereditaria | 2023-07-28 | criteria provided, single submitter | research | |
OMIM | RCV000011432 | SCV000031664 | pathogenic | Atrophia bulborum hereditaria | 1993-11-01 | no assertion criteria provided | literature only |