Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000084921 | SCV002304853 | pathogenic | not provided | 2024-08-15 | criteria provided, single submitter | clinical testing | This sequence change replaces glycine, which is neutral and non-polar, with aspartic acid, which is acidic and polar, at codon 84 of the GPR143 protein (p.Gly84Asp). This variant is not present in population databases (gnomAD no frequency). This missense change has been observed in individuals with oculocutaneous albinism (PMID: 8634705, 12868035, 31574285; Invitae). ClinVar contains an entry for this variant (Variation ID: 98624). An algorithm developed to predict the effect of missense changes on protein structure and function (PolyPhen-2) suggests that this variant is likely to be disruptive. Experimental studies have shown that this missense change affects GPR143 function (PMID: 11115845). For these reasons, this variant has been classified as Pathogenic. |
Retina International | RCV000084921 | SCV000117057 | not provided | not provided | no assertion provided | not provided |