Total submissions: 6
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV000179281 | SCV001774171 | pathogenic | not provided | 2025-01-25 | criteria provided, single submitter | clinical testing | In silico analysis supports that this missense variant has a deleterious effect on protein structure/function; This variant is associated with the following publications: (PMID: 12713581, 23824587, 21735174, 28976636, 19060277, 28451379, 32966289, 31077556, 36087940, 31813138, 31196117, 29437493, 34838614, 38707509) |
Genome- |
RCV001797665 | SCV002040092 | likely pathogenic | Tyrosinase-positive oculocutaneous albinism | 2021-11-07 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV000179281 | SCV002157569 | pathogenic | not provided | 2024-12-02 | criteria provided, single submitter | clinical testing | This sequence change replaces proline, which is neutral and non-polar, with leucine, which is neutral and non-polar, at codon 211 of the OCA2 protein (p.Pro211Leu). This variant is present in population databases (rs190612616, gnomAD 0.06%). This missense change has been observed in individual(s) with oculocutaneous albinism (PMID: 12713581, 28976636, 29437493, 31077556, 31813138). In at least one individual the data is consistent with being in trans (on the opposite chromosome) from a pathogenic variant. ClinVar contains an entry for this variant (Variation ID: 198064). Invitae Evidence Modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) indicates that this missense variant is not expected to disrupt OCA2 protein function with a negative predictive value of 80%. This variant disrupts the p.Pro211 amino acid residue in OCA2. Other variant(s) that disrupt this residue have been observed in individuals with OCA2-related conditions (PMID: 25412400), which suggests that this may be a clinically significant amino acid residue. For these reasons, this variant has been classified as Pathogenic. |
Baylor Genetics | RCV003468870 | SCV004209004 | pathogenic | SKIN/HAIR/EYE PIGMENTATION 1, BLUE/NONBLUE EYES | 2024-02-19 | criteria provided, single submitter | clinical testing | |
Fulgent Genetics, |
RCV005003534 | SCV005630599 | likely pathogenic | Tyrosinase-positive oculocutaneous albinism; SKIN/HAIR/EYE PIGMENTATION 1, BLUE/NONBLUE EYES | 2023-12-22 | criteria provided, single submitter | clinical testing | |
Eurofins Ntd Llc |
RCV000179281 | SCV000231506 | uncertain significance | not provided | 2014-11-18 | flagged submission | clinical testing |