Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Diagnostics Services |
RCV004586421 | SCV005077780 | uncertain significance | Pyruvate dehydrogenase E1-alpha deficiency | 2024-05-31 | criteria provided, single submitter | clinical testing | The c.689G>C variant is not present in publicly available population databases like 1000 Genomes, ExAC, EVS, gnomAD, Indian Exome Database or our in-house exome database. This variant has neither been published in literature in individuals with PDHA1-related conditions nor reported to the clinical databases like Human Genome Mutation Database (HGMD), ClinVar or OMIM, in any affected individuals. In-silico pathogenicity prediction programs like SIFT, PolyPhen-2, MutationTaster2, CADD, Franklin etc predicted the variant to be likely deleterious, however these predictions were not confirmed by published functional studies. This variant is present in a mutational hotspot region of the gene. |