Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Counsyl | RCV000667050 | SCV000791441 | uncertain significance | Rhizomelic chondrodysplasia punctata type 1 | 2017-10-09 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV001855474 | SCV002261228 | uncertain significance | Peroxisome biogenesis disorder 9B | 2022-03-03 | criteria provided, single submitter | clinical testing | This sequence change replaces isoleucine, which is neutral and non-polar, with phenylalanine, which is neutral and non-polar, at codon 245 of the PEX7 protein (p.Ile245Phe). This variant is present in population databases (rs750815894, gnomAD 0.0009%). This missense change has been observed in individuals with rhizomelic chondrodysplasia punctata (PMID: 26408048; Invitae). ClinVar contains an entry for this variant (Variation ID: 551886). Algorithms developed to predict the effect of missense changes on protein structure and function are either unavailable or do not agree on the potential impact of this missense change (SIFT: "Deleterious"; PolyPhen-2: "Possibly Damaging"; Align-GVGD: "Class C0"). In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |