Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
ARUP Laboratories, |
RCV001285095 | SCV001471447 | uncertain significance | Ehlers-Danlos syndrome, kyphoscoliotic type 1 | 2020-06-02 | criteria provided, single submitter | clinical testing | The PLOD1 c.4C>T; p.Arg2Trp variant (rs1402614845), to our knowledge, is not reported in the medical literature or gene-specific databases. This variant is found on only five chromosomes (5/132228 alleles) in the Genome Aggregation Database. The arginine at codon 2 is highly conserved, but computational analyses (SIFT: damaging, PolyPhen-2: benign) predict conflicting effects of this variant on protein structure/function. Due to limited information, the clinical significance of the p.Arg2Trp variant is uncertain at this time. |
Ambry Genetics | RCV004035529 | SCV003990450 | uncertain significance | Familial thoracic aortic aneurysm and aortic dissection | 2023-06-05 | criteria provided, single submitter | clinical testing | The c.4C>T (p.R2W) alteration is located in exon 1 (coding exon 1) of the PLOD1 gene. This alteration results from a C to T substitution at nucleotide position 4, causing the arginine (R) at amino acid position 2 to be replaced by a tryptophan (W). Based on insufficient or conflicting evidence, the clinical significance of this alteration remains unclear. |