Total submissions: 8
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV000485565 | SCV000568194 | uncertain significance | not provided | 2024-12-13 | criteria provided, single submitter | clinical testing | Not observed at significant frequency in large population cohorts (gnomAD); In silico analysis supports that this missense variant has a deleterious effect on protein structure/function; This variant is associated with the following publications: (PMID: 11142762, 11409861, 11058895, 11058896, 34859900, 28122681, 37002680) |
Baylor Genetics | RCV000675138 | SCV001527207 | likely pathogenic | PMM2-congenital disorder of glycosylation | 2024-02-17 | criteria provided, single submitter | clinical testing | |
Mayo Clinic Laboratories, |
RCV000485565 | SCV002520058 | likely pathogenic | not provided | 2021-10-25 | criteria provided, single submitter | clinical testing | PP3, PP4, PM2, PM5 |
Labcorp Genetics |
RCV000675138 | SCV003522707 | pathogenic | PMM2-congenital disorder of glycosylation | 2025-01-05 | criteria provided, single submitter | clinical testing | This sequence change replaces asparagine, which is neutral and polar, with serine, which is neutral and polar, at codon 216 of the PMM2 protein (p.Asn216Ser). This variant is present in population databases (rs78290141, gnomAD 0.004%). This missense change has been observed in individual(s) with congenital disorder of glycosylation (PMID: 11058896, 28122681). ClinVar contains an entry for this variant (Variation ID: 198713). Invitae Evidence Modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) indicates that this missense variant is expected to disrupt PMM2 protein function with a positive predictive value of 95%. This variant disrupts the p.Asn216 amino acid residue in PMM2. Other variant(s) that disrupt this residue have been determined to be pathogenic (PMID: 9140401, 11875054, 25355454). This suggests that this residue is clinically significant, and that variants that disrupt this residue are likely to be disease-causing. For these reasons, this variant has been classified as Pathogenic. |
Fulgent Genetics, |
RCV000675138 | SCV005642481 | likely pathogenic | PMM2-congenital disorder of glycosylation | 2024-04-05 | criteria provided, single submitter | clinical testing | |
Eurofins Ntd Llc |
RCV000485565 | SCV000232515 | uncertain significance | not provided | 2014-06-10 | flagged submission | clinical testing | |
Counsyl | RCV000675138 | SCV000800726 | uncertain significance | PMM2-congenital disorder of glycosylation | 2017-09-26 | flagged submission | clinical testing | |
Natera, |
RCV000675138 | SCV001457179 | likely pathogenic | PMM2-congenital disorder of glycosylation | 2020-09-16 | no assertion criteria provided | clinical testing |