Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Illumina Laboratory Services, |
RCV001270878 | SCV001451655 | uncertain significance | Thrombophilia due to protein C deficiency, autosomal dominant | 2019-02-12 | criteria provided, single submitter | clinical testing | The PROC c.400+5G>C variant is a splice region variant. This variant has been identified in a single heterozygous individual with protein C deficiency with the level of protein C at 58% of normal levels (Bruwer et al. 2016). The variant is not found in the Genome Aggregation Database in a region of good sequencing coverage so the variant is presumed to be rare. Based on the limited evidence, the c.400+5G>C variant is classified as a variant of uncertain significance for protein C deficiency. |
Labcorp Genetics |
RCV001270878 | SCV002201414 | pathogenic | Thrombophilia due to protein C deficiency, autosomal dominant | 2023-09-08 | criteria provided, single submitter | clinical testing | This variant disrupts the c.400+5G nucleotide in the PROC gene. Other variant(s) that disrupt this nucleotide have been determined to be pathogenic (PMID: 1868249, 31254973). This suggests that this nucleotide is clinically significant, and that variants that disrupt this position are likely to be disease-causing. For these reasons, this variant has been classified as Pathogenic. Variants that disrupt the consensus splice site are a relatively common cause of aberrant splicing (PMID: 17576681, 9536098). Algorithms developed to predict the effect of sequence changes on RNA splicing suggest that this variant may disrupt the consensus splice site. This sequence change falls in intron 5 of the PROC gene. It does not directly change the encoded amino acid sequence of the PROC protein. It affects a nucleotide within the consensus splice site. This variant is present in population databases (rs199469478, gnomAD 0.006%). This variant has been observed in individual(s) with protein C deficiency (PMID: 1868249, 2783855; Invitae). In at least one individual the data is consistent with being in trans (on the opposite chromosome) from a pathogenic variant. This variant is also known as 3222 G>C. ClinVar contains an entry for this variant (Variation ID: 989365). |
Mayo Clinic Laboratories, |
RCV003481043 | SCV004224954 | uncertain significance | not provided | 2022-07-11 | criteria provided, single submitter | clinical testing | PP3, PM2 |