Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000546522 | SCV000645562 | pathogenic | PTEN hamartoma tumor syndrome | 2022-10-28 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Pathogenic. Studies have shown that disruption of this splice site results in partial intron inclusion and introduces a premature termination codon (PMID: 11071384). The resulting mRNA is expected to undergo nonsense-mediated decay. ClinVar contains an entry for this variant (Variation ID: 468676). Disruption of this splice site has been observed in individual(s) with juvenile polyposis syndrome and breast cancer and Cowden disease (PMID: 9259288, 17873119, 26681312). It has also been observed to segregate with disease in related individuals. This variant is not present in population databases (gnomAD no frequency). This sequence change affects a donor splice site in intron 4 of the PTEN gene. RNA analysis indicates that disruption of this splice site induces altered splicing and may result in an absent or disrupted protein product. |
Fulgent Genetics, |
RCV000763219 | SCV000893846 | pathogenic | Macrocephaly-autism syndrome; Familial meningioma; Malignant tumor of prostate; VACTERL with hydrocephalus; Glioma susceptibility 2; PTEN hamartoma tumor syndrome; Cowden syndrome 1 | 2018-10-31 | criteria provided, single submitter | clinical testing | |
Prevention |
RCV004722901 | SCV005339198 | pathogenic | PTEN-related disorder | 2024-06-18 | no assertion criteria provided | clinical testing | The PTEN c.253+2T>A variant is predicted to disrupt the GT donor site and interfere with normal splicing. To our knowledge this variant has not been reported in literature; however, alternative splice variants in the same canonical splice donor site (c.253+1G>A, c.253+1G>C, c.253+1G>T, and c.253+2T>C) have been reported in individuals with PTEN-related disorders (Busch et al. 2013. PubMed ID: 23470840; Table S1, Susswein et al. 2016. PubMed ID: 26681312; Celebi et al. 2000. PubMed ID: 11071384; Human Gene Mutation Database, http://www.hgmd.cf.ac.uk/ac/index.php). This variant has not been reported in a large population database, indicating this variant is rare. Variants that disrupt the consensus splice donor site in PTEN are expected to be pathogenic. This variant is interpreted as pathogenic. |