Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
DASA | RCV002221476 | SCV002499417 | likely pathogenic | Familial hypoparathyroidism | 2022-04-10 | criteria provided, single submitter | clinical testing | The c.247C>T;p.(Arg83*) variant creates a premature translational stop signal in the PTH gene without sufficient information about prediction of nonsense mediated mRNA decay (NMD) type change; it is present in a relevant exon to the transcript, and disrupts >10% of the protein product - PVS1_strong. This sequence change has been observed in affected individual(s) (PMID: 18784115; 1425431) - PS4_supporting. The variant is present at low allele frequencies population databases (rs6256 – gnomAD 0.00003978%; ABraOM no frequency - https://abraom.ib.usp.br/) - PM2_supporting. In summary, the currently available evidence indicates that the variant is likely pathogenic. |
OMIM | RCV000014767 | SCV000035022 | pathogenic | Primary hyperparathyroidism | 2008-09-11 | no assertion criteria provided | literature only |