Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV001756428 | SCV001985181 | uncertain significance | not provided | 2020-10-08 | criteria provided, single submitter | clinical testing | Not observed at a significant frequency in large population cohorts (Lek et al., 2016); In silico analysis supports that this missense variant does not alter protein structure/function; This variant is associated with the following publications: (PMID: 20059486, 32202960, 32651154, 33234470) |
Fulgent Genetics, |
RCV002477922 | SCV002784558 | uncertain significance | 6-Pyruvoyl-tetrahydrobiopterin synthase deficiency | 2021-09-17 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV002477922 | SCV003440323 | pathogenic | 6-Pyruvoyl-tetrahydrobiopterin synthase deficiency | 2022-05-03 | criteria provided, single submitter | clinical testing | ClinVar contains an entry for this variant (Variation ID: 1302929). This sequence change replaces valine, which is neutral and non-polar, with alanine, which is neutral and non-polar, at codon 103 of the PTS protein (p.Val103Ala). This variant is present in population databases (no rsID available, gnomAD 0.0009%). This missense change has been observed in individual(s) with 6-pyruvoyl-tetrahydropterin synthase deficiency (PMID: 20059486, 33234470). In at least one individual the data is consistent with being in trans (on the opposite chromosome) from a pathogenic variant. It has also been observed to segregate with disease in related individuals. Algorithms developed to predict the effect of missense changes on protein structure and function (SIFT, PolyPhen-2, Align-GVGD) all suggest that this variant is likely to be tolerated. For these reasons, this variant has been classified as Pathogenic. |
Baylor Genetics | RCV002477922 | SCV004207166 | pathogenic | 6-Pyruvoyl-tetrahydrobiopterin synthase deficiency | 2023-03-25 | criteria provided, single submitter | clinical testing |