Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000557581 | SCV000631815 | pathogenic | Dihydropteridine reductase deficiency | 2023-09-06 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Pathogenic. An algorithm developed to predict the effect of missense changes on protein structure and function (PolyPhen-2) suggests that this variant is likely to be disruptive. ClinVar contains an entry for this variant (Variation ID: 459896). This missense change has been observed in individual(s) with BH4 deficiency (PMID: 26006720). This variant is present in population databases (no rsID available, gnomAD 0.002%). This sequence change replaces serine, which is neutral and polar, with leucine, which is neutral and non-polar, at codon 115 of the QDPR protein (p.Ser115Leu). |
Pathology and Clinical Laboratory Medicine, |
RCV000557581 | SCV001438941 | likely pathogenic | Dihydropteridine reductase deficiency | criteria provided, single submitter | clinical testing | ||
Gene |
RCV003322781 | SCV004028371 | likely pathogenic | not provided | 2023-02-21 | criteria provided, single submitter | clinical testing | Observed with a second QDPR variant in a patient with BH4-deficient hyperphenylalaninemia in published literature, but it is not known whether the variants occurred on the same (in cis) or on different (in trans) chromosomes (Gundorova et al., 2021); Not observed at significant frequency in large population cohorts (gnomAD); In silico analysis supports that this missense variant has a deleterious effect on protein structure/function; This variant is associated with the following publications: (PMID: 33152132, 27527004, 33903016, 26006720, 27246466, 33822819) |
Fulgent Genetics, |
RCV000557581 | SCV005662073 | likely pathogenic | Dihydropteridine reductase deficiency | 2024-03-16 | criteria provided, single submitter | clinical testing |