Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Illumina Laboratory Services, |
RCV003985160 | SCV004801462 | likely pathogenic | Dihydropteridine reductase deficiency | 2020-04-28 | criteria provided, single submitter | clinical testing | The QDPR c.49G>A p.(Gly17Ser) missense variant has not, to our knowledge, been reported in the peer-reviewed literature. This variant is not observed in version 2.1.1 of the Genome Aggregation Database. The p.Gly17Ser variant occurs in a hotspot region of the QDPR gene that includes several variants at the Gly17 residue, including one found in a compound heterozygous state with a null allele in an affected individual (Smooker et al. 1999; Al-Jasmi et al. 2015; Foroozani et al. 2015). Multiple lines of computational evidence suggest the variant may impact the gene or gene product. Based on the collective evidence the c.49G>A p.(Gly17Ser) variant is classified as likely pathogenic for BH4-deficient hyperphenylalaninemia. |