Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001066595 | SCV001231610 | pathogenic | Retinoblastoma | 2019-11-21 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Pathogenic. Loss-of-function variants in RB1 are known to be pathogenic (PMID: 17096365). This variant has been observed in an individual affected with retinoblastoma (PMID: 12955724). This variant is also known as g.153284C>T in the literature. This variant is not present in population databases (ExAC no frequency). This sequence change creates a premature translational stop signal (p.Gln631*) in the RB1 gene. It is expected to result in an absent or disrupted protein product. |
ARUP Laboratories, |
RCV003117734 | SCV003799553 | pathogenic | not provided | 2022-03-31 | criteria provided, single submitter | clinical testing | The RB1 c.1891C>T; p.Gln631Ter variant (rs1217977493) is reported in the literature in an individual with retinoblastoma (Kiran 2003). The variant is listed in the ClinVar database (Variation ID: 860313), but is absent from the Genome Aggregation Database, indicating it is not a common polymorphism. This variant induces an early termination codon and is predicted to result in a truncated protein or mRNA subject to nonsense-mediated decay. Additionally, several downstream truncating variants have been described in individuals with retinoblastoma and are considered pathogenic (Taylor 2007). Based on available information, this variant is classified as pathogenic. References: Kiran VS et al. Mutational screening of the RB1 gene in Indian patients with retinoblastoma reveals eight novel and several recurrent mutations. Hum Mutat. 2003 Oct;22(4):339. PMID: 12955724. Taylor M et al. Genotype-phenotype correlations in hereditary familial retinoblastoma. Hum Mutat. 2007 Mar;28(3):284-93. PMID: 17096365. |
Genetic Diagnostic Laboratory, |
RCV001066595 | SCV005046216 | pathogenic | Retinoblastoma | 2024-05-20 | criteria provided, single submitter | clinical testing | Case and Pedigree Information: BILATERAL CASES:1, UNILATERAL CASES:0, TOTAL CASES:1, PEDIGREES:1. ACMG Codes Applied:PVS1, PM2 |