Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001388978 | SCV001590173 | pathogenic | PRPH2-related disorder | 2022-09-02 | criteria provided, single submitter | clinical testing | This missense change has been observed in individuals with autosomal dominant retinitis pigmentosa (PMID: 9673478, 25447119). It has also been observed to segregate with disease in related individuals. For these reasons, this variant has been classified as Pathogenic. Experimental studies have shown that this missense change affects PRPH2 function (PMID: 10747861). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is expected to disrupt PRPH2 protein function. ClinVar contains an entry for this variant (Variation ID: 98672). This variant is not present in population databases (gnomAD no frequency). This sequence change replaces cysteine, which is neutral and slightly polar, with tyrosine, which is neutral and polar, at codon 165 of the PRPH2 protein (p.Cys165Tyr). |
Retina International | RCV000084976 | SCV000117112 | not provided | not provided | no assertion provided | not provided | ||
Leiden Open Variation Database | RCV000084976 | SCV001744952 | likely pathogenic | not provided | 2021-04-06 | no assertion criteria provided | curation | Curator: Global Variome, with Curator vacancy. Submitter to LOVD: Manon Peeters. |