Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Retina International | RCV000084995 | SCV000117131 | not provided | not provided | no assertion provided | not provided | ||
Leiden Open Variation Database | RCV000084995 | SCV001744982 | pathogenic | not provided | 2021-04-06 | no assertion criteria provided | curation | Curator: Global Variome, with Curator vacancy. Submitter to LOVD: Manon Peeters. |
Prevention |
RCV004724802 | SCV005338441 | pathogenic | PRPH2-related disorder | 2024-08-30 | no assertion criteria provided | clinical testing | The PRPH2 c.623dupG variant is predicted to result in a frameshift and premature protein termination (p.Val209Argfs*9). This variant has been reported in the heterozygous state in individuals with presumably autosomal dominant retinal disease (referred to as Gly208insG, Kohl et al. 1997. PubMed ID: 9279751; Table S2, Peeters et al. 2021. PubMed ID: 34411390). This variant has not been reported in a large population database, indicating this variant is rare. Frameshift variants in PRPH2 are an established mechanism of disease. Given the evidence, we interpret this variant as pathogenic for autosomal dominant disease. |