Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001873756 | SCV002237739 | pathogenic | PRPH2-related disorder | 2021-08-05 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Pathogenic. This variant disrupts a region of the PRPH2 protein in which other variant(s) (p.Trp316*) have been observed in individuals with PRPH2-related conditions (PMID: 9338584). This suggests that this is a clinically significant region of the protein, and that variants that disrupt it are likely to be disease-causing. ClinVar contains an entry for this variant (Variation ID: 1175277). This premature translational stop signal has been observed in individuals with autosomal dominant retinitis pigmentosa (PMID: 24938718). It has also been observed to segregate with disease in related individuals. This variant is not present in population databases (ExAC no frequency). This sequence change creates a premature translational stop signal (p.Gly305Alafs*19) in the PRPH2 gene. While this is not anticipated to result in nonsense mediated decay, it is expected to disrupt the last 42 amino acid(s) of the PRPH2 protein. |
Juno Genomics, |
RCV004819243 | SCV005440650 | pathogenic | Retinitis pigmentosa 7; Pigmentary retinal dystrophy; Patterned macular dystrophy 1; Choroidal dystrophy, central areolar 2; Vitelliform macular dystrophy 3 | criteria provided, single submitter | clinical testing | PM2_Supporting+PVS1_Strong+PS4_Moderate+PP1_Strong | |
Leiden Open Variation Database | RCV001530335 | SCV001745124 | pathogenic | not provided | 2021-04-06 | no assertion criteria provided | curation | Curator: Global Variome, with Curator vacancy. Submitter to LOVD: Manon Peeters. |