Total submissions: 9
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV003654190 | SCV000637081 | uncertain significance | not provided | 2024-01-31 | criteria provided, single submitter | clinical testing | This sequence change replaces glutamic acid, which is acidic and polar, with lysine, which is basic and polar, at codon 462 of the SCN5A protein (p.Glu462Lys). This variant is present in population databases (rs199473572, gnomAD 0.007%). This missense change has been observed in individuals with SCN5A-related conditions (PMID: 15840476, 19841300, 24721456, 31737537). ClinVar contains an entry for this variant (Variation ID: 67660). An algorithm developed to predict the effect of missense changes on protein structure and function (PolyPhen-2) suggests that this variant is likely to be disruptive. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Color Diagnostics, |
RCV001842279 | SCV001356061 | uncertain significance | Cardiac arrhythmia | 2023-12-13 | criteria provided, single submitter | clinical testing | This missense variant replaces glutamic acid with lysine at codon 462 of the SCN5A protein. Computational prediction suggests that this variant may have deleterious impact on protein structure and function (internally defined REVEL score threshold >= 0.7, PMID: 27666373). To our knowledge, functional studies have not been reported for this variant. This variant has been reported in an individual affected with Brugada syndrome (PMID: 24721456), in a few individual affected with or suspected of having long QT syndrome (PMID: 15840476, 19841300, 31737537), and in an individual affected with dilated cardiomyopathy (PMID: 37904629). This variant has been identified in 7/248440 chromosomes in the general population by the Genome Aggregation Database (gnomAD). The available evidence is insufficient to determine the role of this variant in disease conclusively. Therefore, this variant is classified as a Variant of Uncertain Significance. |
MGZ Medical Genetics Center | RCV002288556 | SCV002580684 | uncertain significance | Brugada syndrome 1 | 2022-01-18 | criteria provided, single submitter | clinical testing | |
Fulgent Genetics, |
RCV002504969 | SCV002796912 | uncertain significance | Brugada syndrome 1; Long QT syndrome 3; Sick sinus syndrome 1; Progressive familial heart block, type 1A; Ventricular fibrillation, paroxysmal familial, type 1; Dilated cardiomyopathy 1E; SUDDEN INFANT DEATH SYNDROME; Atrial fibrillation, familial, 10 | 2021-10-09 | criteria provided, single submitter | clinical testing | |
Institute of Immunology and Genetics Kaiserslautern | RCV003509485 | SCV004363640 | uncertain significance | Long QT syndrome 3 | 2024-01-29 | criteria provided, single submitter | clinical testing | ACMG Criteria: PM2_P,PP3,PP5; Variant was found in heterozygous state |
Ambry Genetics | RCV004019032 | SCV004943814 | uncertain significance | Cardiovascular phenotype | 2022-09-13 | criteria provided, single submitter | clinical testing | The c.1384G>A (p.E462K) alteration is located in exon 11 (coding exon 10) of the SCN5A gene. This alteration results from a G to A substitution at nucleotide position 1384, causing the glutamic acid (E) at amino acid position 462 to be replaced by a lysine (K). Based on insufficient or conflicting evidence, the clinical significance of this alteration remains unclear. |
Breakthrough Genomics, |
RCV003654190 | SCV005189604 | uncertain significance | not provided | criteria provided, single submitter | not provided | ||
Cardiovascular Biomedical Research Unit, |
RCV000058419 | SCV000089939 | not provided | Congenital long QT syndrome | no assertion provided | literature only | This variant has been reported as associated with Long QT syndrome in the following publications (PMID:15840476;PMID:19841300;PMID:22378279). This is a literature report, and does not necessarily reflect the clinical interpretation of the Imperial College / Royal Brompton Cardiovascular Genetics laboratory. | |
CSER _CC_NCGL, |
RCV000148862 | SCV000190606 | uncertain significance | Long QT syndrome | 2014-06-01 | no assertion criteria provided | research |