Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV003226960 | SCV000760231 | uncertain significance | not provided | 2024-10-18 | criteria provided, single submitter | clinical testing | This sequence change replaces serine, which is neutral and polar, with alanine, which is neutral and non-polar, at codon 835 of the SCN5A protein (p.Ser835Ala). This variant is present in population databases (no rsID available, gnomAD 0.01%). This missense change has been observed in individual(s) with Brugada syndrome (PMID: 34930020). ClinVar contains an entry for this variant (Variation ID: 532087). An algorithm developed to predict the effect of missense changes on protein structure and function (PolyPhen-2) suggests that this variant is likely to be disruptive. Experimental studies have shown that this missense change affects SCN5A function (PMID: 34930020). In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Gene |
RCV003226960 | SCV003923971 | uncertain significance | not provided | 2022-11-08 | criteria provided, single submitter | clinical testing | Reported in an individual with atrial fibrillation (Glazer et al., 2022); Not observed at significant frequency in large population cohorts (gnomAD); In vitro functional analysis demonstrated electrophysiological function similar to wild type (Glazer et al., 2022); In silico analysis supports that this missense variant has a deleterious effect on protein structure/function; This variant is associated with the following publications: (PMID: 34930020) |
All of Us Research Program, |
RCV004003855 | SCV004842935 | uncertain significance | Cardiac arrhythmia | 2024-09-23 | criteria provided, single submitter | clinical testing | |
Ambry Genetics | RCV004025522 | SCV005031214 | uncertain significance | Cardiovascular phenotype | 2023-11-21 | criteria provided, single submitter | clinical testing | The p.S835A variant (also known as c.2503T>G), located in coding exon 15 of the SCN5A gene, results from a T to G substitution at nucleotide position 2503. The serine at codon 835 is replaced by alanine, an amino acid with similar properties. This variant has been detected in an individual with atrial fibrillation; in vitro analyses from the same group indicated this variant may not impact peak channel current compared to wild type; however, additional evidence is needed to confirm this finding (Glazer AM et al. Circulation, 2022 Mar;145:877-891). This amino acid position is highly conserved in available vertebrate species. In addition, this alteration is predicted to be deleterious by in silico analysis. Since supporting evidence is limited at this time, the clinical significance of this alteration remains unclear. |