Total submissions: 5
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000085388 | SCV001229072 | pathogenic | not provided | 2023-07-17 | criteria provided, single submitter | clinical testing | This sequence change replaces serine, which is neutral and polar, with arginine, which is basic and polar, at codon 445 of the ABCA4 protein (p.Ser445Arg). This variant is present in population databases (rs61748552, gnomAD 0.002%). This missense change has been observed in individuals with Stargardt disease (PMID: 26872967, 28041643; Invitae). ClinVar contains an entry for this variant (Variation ID: 99045). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is expected to disrupt ABCA4 protein function. For these reasons, this variant has been classified as Pathogenic. |
Blueprint Genetics | RCV000210294 | SCV001239905 | likely pathogenic | Retinal dystrophy | 2019-07-10 | criteria provided, single submitter | clinical testing | |
Retina International | RCV000085388 | SCV000117525 | not provided | not provided | no assertion provided | not provided | ||
Centre for Genomic Medicine, |
RCV000210294 | SCV000259079 | likely pathogenic | Retinal dystrophy | 2015-01-21 | no assertion criteria provided | clinical testing | |
NIHR Bioresource Rare Diseases, |
RCV000504649 | SCV000598932 | likely pathogenic | Severe early-childhood-onset retinal dystrophy | 2015-01-01 | no assertion criteria provided | research |