Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000085550 | SCV003523334 | pathogenic | not provided | 2024-03-13 | criteria provided, single submitter | clinical testing | This sequence change replaces glycine, which is neutral and non-polar, with aspartic acid, which is acidic and polar, at codon 1050 of the ABCA4 protein (p.Gly1050Asp). This variant is present in population databases (rs61750062, gnomAD 0.004%). This missense change has been observed in individual(s) with Stargardt disease (PMID: 11702214). In at least one individual the data is consistent with being in trans (on the opposite chromosome) from a pathogenic variant. It has also been observed to segregate with disease in related individuals. ClinVar contains an entry for this variant (Variation ID: 99199). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is expected to disrupt ABCA4 protein function with a positive predictive value of 95%. For these reasons, this variant has been classified as Pathogenic. |
Institute of Human Genetics, |
RCV004815099 | SCV005070500 | likely pathogenic | Retinal dystrophy | 2016-01-01 | criteria provided, single submitter | clinical testing | |
Fulgent Genetics, |
RCV005025154 | SCV005659392 | likely pathogenic | Cone-rod dystrophy 3; Age related macular degeneration 2; Severe early-childhood-onset retinal dystrophy; Retinitis pigmentosa 19 | 2024-06-13 | criteria provided, single submitter | clinical testing | |
Retina International | RCV000085550 | SCV000117687 | not provided | not provided | no assertion provided | not provided |