Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV000483369 | SCV000564538 | likely pathogenic | not provided | 2013-07-31 | criteria provided, single submitter | clinical testing | The c.5836-3 C>A variant in the ABCA4 gene has not been reported as a pathogenic mutation or as a benign polymorphism to our knowledge. Three in silico splice prediction algorithms predict c.5836-3 C>A destroys or damages the natural splice acceptor site of intron 41. The c.5836-3 C>A variant was not observed in approximately 6,500 individuals of European and African American ancestry in an external variant database, indicating it is not a common benign variant in these populations. Therefore, the c.5836-3C>A variant is a candidate for a pathogenic variant, although the possibility that it is a benign polymorphism cannot be completely excluded. |
Labcorp Genetics |
RCV000483369 | SCV003523329 | uncertain significance | not provided | 2022-07-01 | criteria provided, single submitter | clinical testing | This sequence change falls in intron 41 of the ABCA4 gene. It does not directly change the encoded amino acid sequence of the ABCA4 protein. It affects a nucleotide within the consensus splice site. This variant is not present in population databases (gnomAD no frequency). This variant has been observed in individual(s) with ABCA4-related conditions (PMID: 25082829). ClinVar contains an entry for this variant (Variation ID: 417993). Variants that disrupt the consensus splice site are a relatively common cause of aberrant splicing (PMID: 17576681, 9536098). Studies have shown that this variant is associated with altered splicing resulting in the insertion of 30 nucleotides into the transcript (PMID: 29162642, 32413971). In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Rui Chen Lab, |
RCV000515665 | SCV000579423 | pathogenic | Retinitis pigmentosa | 2017-05-09 | no assertion criteria provided | research |