Total submissions: 6
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Invitae | RCV000525235 | SCV000641488 | likely benign | Tuberous sclerosis 1 | 2024-01-22 | criteria provided, single submitter | clinical testing | |
Ambry Genetics | RCV001010403 | SCV001170601 | uncertain significance | Hereditary cancer-predisposing syndrome | 2024-03-15 | criteria provided, single submitter | clinical testing | The p.L41F variant (also known as c.121C>T), located in coding exon 2 of the TSC1 gene, results from a C to T substitution at nucleotide position 121. The leucine at codon 41 is replaced by phenylalanine, an amino acid with highly similar properties. This amino acid position is highly conserved in available vertebrate species. In addition, this alteration is predicted to be deleterious by in silico analysis. Since supporting evidence is limited at this time, the clinical significance of this alteration remains unclear. |
Genome- |
RCV000525235 | SCV002040182 | likely benign | Tuberous sclerosis 1 | 2021-11-07 | criteria provided, single submitter | clinical testing | |
Sema4, |
RCV001010403 | SCV002530886 | uncertain significance | Hereditary cancer-predisposing syndrome | 2021-05-06 | criteria provided, single submitter | curation | |
Prevention |
RCV003424114 | SCV004108466 | uncertain significance | TSC1-related disorder | 2023-08-28 | criteria provided, single submitter | clinical testing | The TSC1 c.121C>T variant is predicted to result in the amino acid substitution p.Leu41Phe. To our knowledge, this variant has not been reported in the literature. This variant is reported in 0.00088% of alleles in individuals of European (Non-Finnish) descent in gnomAD (http://gnomad.broadinstitute.org/variant/9-135802677-G-A). At this time, the clinical significance of this variant is uncertain due to the absence of conclusive functional and genetic evidence. |
All of Us Research Program, |
RCV003999185 | SCV004840567 | uncertain significance | Tuberous sclerosis syndrome | 2024-01-11 | criteria provided, single submitter | clinical testing | This missense variant replaces leucine with phenylalanine at codon 41 of the TSC1 protein. Computational prediction suggests that this variant may have deleterious impact on protein structure and function (internally defined REVEL score threshold >= 0.7, PMID: 27666373). To our knowledge, functional studies have not been reported for this variant. This variant has not been reported in individuals affected with TSC1-related disorders in the literature. This variant has been identified in 1/251120 chromosomes in the general population by the Genome Aggregation Database (gnomAD). The available evidence is insufficient to determine the role of this variant in disease conclusively. Therefore, this variant is classified as a Variant of Uncertain Significance. |