Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001852868 | SCV002280682 | likely pathogenic | Tuberous sclerosis 1 | 2022-01-16 | criteria provided, single submitter | clinical testing | Algorithms developed to predict the effect of missense changes on protein structure and function are either unavailable or do not agree on the potential impact of this missense change (SIFT: "Deleterious"; PolyPhen-2: "Probably Damaging"; Align-GVGD: "Class C0"). Experimental studies have shown that this missense change affects TSC1 function (PMID: 21309039). In summary, the currently available evidence indicates that the variant is pathogenic, but additional data are needed to prove that conclusively. Therefore, this variant has been classified as Likely Pathogenic. ClinVar contains an entry for this variant (Variation ID: 49060). This sequence change replaces leucine, which is neutral and non-polar, with histidine, which is basic and polar, at codon 191 of the TSC1 protein (p.Leu191His). This variant is not present in population databases (gnomAD no frequency). This missense change has been observed in individual(s) with tuberous sclerosis complex (PMID: 10227394, 18830229). In at least one individual the variant was observed to be de novo. |
Tuberous sclerosis database |
RCV000042313 | SCV000066102 | not provided | Tuberous sclerosis syndrome | no assertion provided | curation |