Total submissions: 7
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Genetic Services Laboratory, |
RCV000503855 | SCV000597795 | pathogenic | Tyrosinase-negative oculocutaneous albinism | 2016-03-29 | criteria provided, single submitter | clinical testing | |
Ce |
RCV001092183 | SCV001248571 | pathogenic | not provided | 2018-10-01 | criteria provided, single submitter | clinical testing | |
Genome- |
RCV000503855 | SCV001821955 | pathogenic | Tyrosinase-negative oculocutaneous albinism | 2021-07-22 | criteria provided, single submitter | clinical testing | |
Molecular Diagnostics Laboratory, |
RCV001730694 | SCV001981545 | pathogenic | Oculocutaneous albinism type 1 | 2021-08-17 | criteria provided, single submitter | clinical testing | |
MGZ Medical Genetics Center | RCV000503855 | SCV002579801 | likely pathogenic | Tyrosinase-negative oculocutaneous albinism | 2022-02-24 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV001092183 | SCV004296115 | pathogenic | not provided | 2024-09-24 | criteria provided, single submitter | clinical testing | This sequence change creates a premature translational stop signal (p.Gly346*) in the TYR gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in TYR are known to be pathogenic (PMID: 23504663). This variant is present in population databases (no rsID available, gnomAD 0.003%). This premature translational stop signal has been observed in individual(s) with clinical features of ocular albinism (PMID: 8026428). ClinVar contains an entry for this variant (Variation ID: 437179). Algorithms developed to predict the effect of sequence changes on RNA splicing suggest that this variant may disrupt the consensus splice site. For these reasons, this variant has been classified as Pathogenic. |
Baylor Genetics | RCV004568641 | SCV005054557 | pathogenic | SKIN/HAIR/EYE PIGMENTATION 3, LIGHT/DARK SKIN | 2024-03-30 | criteria provided, single submitter | clinical testing |