Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Women's Health and Genetics/Laboratory Corporation of America, |
RCV003988464 | SCV004804525 | uncertain significance | not specified | 2024-01-12 | criteria provided, single submitter | clinical testing | Variant summary: TYR c.1556_1557delAG (p.Glu519GlyfsX27) causes a frameshift which results in an extension of the protein. The variant allele was found at a frequency of 8e-05 in 275138 control chromosomes, predominantly at a frequency of 0.00089 within the African or African-American subpopulation in the gnomAD database. This frequency is not significantly higher than estimated for a pathogenic variant in TYR causing Oculocutaneous Albinism (8e-05 vs 0.0056), allowing no conclusion about variant significance. To our knowledge, no occurrence of c.1556_1557delAG in individuals affected with Oculocutaneous Albinism and no experimental evidence demonstrating its impact on protein function have been reported. No submitters have cited clinical-significance assessments for this variant to ClinVar. Based on the evidence outlined above, the variant was classified as uncertain significance. |
Fulgent Genetics, |
RCV005003748 | SCV005631399 | uncertain significance | Tyrosinase-negative oculocutaneous albinism; Oculocutaneous albinism type 1B; SKIN/HAIR/EYE PIGMENTATION 3, LIGHT/DARK SKIN | 2024-04-23 | criteria provided, single submitter | clinical testing |