Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001851634 | SCV002233173 | pathogenic | not provided | 2021-03-27 | criteria provided, single submitter | clinical testing | This sequence change falls in intron 1 of the UROS gene. It does not directly change the encoded amino acid sequence of the UROS protein. The frequency data for this variant in the population databases is considered unreliable, as metrics indicate insufficient coverage at this position in the ExAC database. This variant has been observed in individual(s) with congenital erythropoietic porphyria (PMID: 11254675). In at least one individual the data is consistent with the variant being in trans (on the opposite chromosome) from a pathogenic variant. This variant is also known as -86C>A. ClinVar contains an entry for this variant (Variation ID: 3764). Experimental studies have shown that this variant affects UROS protein function (PMID: 11254675). For these reasons, this variant has been classified as Pathogenic. |
OMIM | RCV000003962 | SCV000024127 | pathogenic | Cutaneous porphyria | 2001-03-01 | no assertion criteria provided | literature only |