Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001851636 | SCV002234736 | pathogenic | not provided | 2021-07-21 | criteria provided, single submitter | clinical testing | This sequence change affects a donor splice site in intron 2 of the UROS gene. RNA analysis indicates that this variant induces altered splicing and likely results in a shortened protein product. This variant is present in population databases (rs373864821, ExAC 0.01%). This variant has been observed in individual(s) with congenital erythropoietic porphyria (PMID: 7860775, 11254675). ClinVar contains an entry for this variant (Variation ID: 3767). Studies have shown that this variant is associated with skipping of exon 2 and is expected to result in the loss of the initiator methionine (PMID: 7860775). This variant disrupts the p.Val3 amino acid residue in UROS. Other variant(s) that disrupt this residue have been determined to be pathogenic (PMID: 9188670, 23626549, 19099412, Invitae). This suggests that this residue is clinically significant, and that variants that disrupt this residue are likely to be disease-causing. For these reasons, this variant has been classified as Pathogenic. |
Prevention |
RCV003407268 | SCV004115651 | likely pathogenic | UROS-related disorder | 2023-06-05 | criteria provided, single submitter | clinical testing | The UROS c.63+1G>A variant is predicted to disrupt the GT donor site and interfere with normal splicing. This variant was reported in an individual with Porphyria, erythropoietic (IVS2+1 in Xu et al. 1995. PubMed ID: 7860775; Solis et al. 2001. PubMed ID: 11254675). This variant is reported in 0.0070% of alleles in individuals of European (Non-Finnish) descent in gnomAD (http://gnomad.broadinstitute.org/variant/10-127505005-C-T). Variants that disrupt the consensus splice donor site in UROS are expected to be pathogenic. This variant is interpreted as likely pathogenic. |
OMIM | RCV000003965 | SCV000024130 | pathogenic | Cutaneous porphyria | 2001-03-01 | no assertion criteria provided | literature only |