Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001960703 | SCV002233106 | pathogenic | Polyglandular autoimmune syndrome, type 1 | 2022-04-25 | criteria provided, single submitter | clinical testing | This sequence change creates a premature translational stop signal (p.Gln69*) in the AIRE gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in AIRE are known to be pathogenic (PMID: 11524731, 26141571). This variant is not present in population databases (gnomAD no frequency). This premature translational stop signal has been observed in individual(s) with hypoparathyroidism (PMID: 31433868). For these reasons, this variant has been classified as Pathogenic. |
Prevention |
RCV004754818 | SCV005354330 | pathogenic | AIRE-related disorder | 2024-05-22 | no assertion criteria provided | clinical testing | The AIRE c.205C>T variant is predicted to result in premature protein termination (p.Gln69*). This variant has been reported in an individual with hypoparathyroidism (Table 1, Wang et al. 2019. PubMed ID: 31433868). This variant has not been reported in a large population database, indicating this variant is rare. Nonsense variants in AIRE are expected to be pathogenic. This variant is interpreted as pathogenic. |