Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Athena Diagnostics | RCV000518668 | SCV000612662 | uncertain significance | not specified | 2016-11-29 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV002527461 | SCV003525279 | uncertain significance | Familial hypocalciuric hypercalcemia; Autosomal dominant hypocalcemia 1 | 2022-02-18 | criteria provided, single submitter | clinical testing | Experimental studies have shown that this missense change affects CASR function (PMID: 31063613). This sequence change replaces alanine, which is neutral and non-polar, with valine, which is neutral and non-polar, at codon 840 of the CASR protein (p.Ala840Val). This variant is not present in population databases (gnomAD no frequency). This missense change has been observed in individuals with hypocalcemia and/or hypoparathyroidism (PMID: 19549694, 24948345, 31063613; Invitae). ClinVar contains an entry for this variant (Variation ID: 446993). Algorithms developed to predict the effect of missense changes on protein structure and function are either unavailable or do not agree on the potential impact of this missense change (SIFT: "Deleterious"; PolyPhen-2: "Possibly Damaging"; Align-GVGD: "Class C0"). In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |