Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Genomic Medicine Center of Excellence, |
RCV000171441 | SCV000221639 | likely pathogenic | not provided | criteria provided, single submitter | research | ||
Gene |
RCV000171441 | SCV000680506 | pathogenic | not provided | 2017-01-13 | criteria provided, single submitter | clinical testing | The E382X nonsense variant in the CHM gene has been reported previously in association with sporadic retinal dystrophy (Patel et al., 2016). This variant is predicted to cause loss of normal protein function either through protein truncation or nonsense-mediated mRNA decay. The variant was not observed in approximately 6,500 individuals of European and African American ancestry in the NHLBI Exome Sequencing Project, indicating it is not a common benign variant in these populations. Therefore, we consider this variant to be pathogenic. |