Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Diagnostics Services |
RCV001799560 | SCV002043743 | likely pathogenic | Xeroderma pigmentosum, group D; Trichothiodystrophy 1, photosensitive | 2021-06-15 | criteria provided, single submitter | clinical testing | The c.1972C>G variant is not present in publicly available population databases like 1000 Genomes, Exome Variant Server (EVS), Exome Aggregation Consortium (ExAC), Genome Aggregation Database (gnomAD) and dbSNP. The variant is also not present in Indian Exome Database and in our in-house exome database. UniProt classifies this variant as Pathogenic, associated with photosensitive trichothiodystrophy-1 (ID: VAR_017290). The variant was earlier identified in patients affected with xeroderma pigmentosum complementation group D and photosensitive trichothiodystrophy-1 (PMID- 7920640, 8571952, 9195225, 9238033, 9758621, 11242112). Alternative variants in the same amino acid position were reported to HGMD (IDs: CM013903, CM960514), ClinVar (Accession: VCV000016785.1) and OMIM (ID: 126340.0007) databases. In-silico pathogenicity prediction programs like SIFT, Polyphen-2, MutationTaster2, CADD, Varsome, InterVar etc. predicted this variant to be likely deleterious. |