Total submissions: 6
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Clin |
RCV002479042 | SCV005903396 | benign | Bernard Soulier syndrome | 2025-02-11 | reviewed by expert panel | curation | The NM_000407.5(GP1BB):c.119G>A variant in GP1BB is a missense variant predicted to cause substitution of glycine by glutamate at amino acid 40 (p.Gly40Glu). The Grpmax Filtering allele frequency in gnomAD v4.1 is 0.002267 (based on 133/50540 alleles) in the Admixed American population, which is higher than the ClinGen PD VCEP threshold (>0.001), and therefore meets this criterion (BA1). This variant has not been reported in relation to Bernard-Soulier Syndrome but is a known platelet antigen (HPA-12b, originally reported as Iy(a) in PMID: 10688847). In summary, this variant meets the criteria to be classified as Benign for autosomal recessive Bernard-Soulier syndrome based on the ACMG/AMP criteria applied, as specified by the ClinGen PD VCEP: BA1. |
Labcorp Genetics |
RCV000906639 | SCV001051290 | benign | not provided | 2019-12-31 | criteria provided, single submitter | clinical testing | |
Fulgent Genetics, |
RCV002479042 | SCV002802553 | likely benign | Bernard Soulier syndrome | 2022-04-11 | criteria provided, single submitter | clinical testing | |
Ce |
RCV000906639 | SCV004698755 | likely benign | not provided | 2024-01-01 | criteria provided, single submitter | clinical testing | GP1BB: PP3, BS2 |
Gene |
RCV000906639 | SCV005333177 | uncertain significance | not provided | 2023-12-10 | criteria provided, single submitter | clinical testing | In silico analysis supports that this missense variant does not alter protein structure/function; This variant is associated with the following publications: (PMID: 28377559, 19548962, 24685245, 25370924, 28983057) |
Mayo Clinic Laboratories, |
RCV000906639 | SCV005410190 | uncertain significance | not provided | 2024-05-29 | criteria provided, single submitter | clinical testing | BS1, PM1_supporting |