Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Clin |
RCV002511539 | SCV002820934 | pathogenic | Glanzmann thrombasthenia | 2022-11-15 | reviewed by expert panel | curation | NM_000419.5(ITGA2B):c.1555C>T (p.Gln519Ter) found in a homozygous proband (PMID:31029159) causes a premature stop codon at exon 16 and is predicted to undergo nonsense mediated decay (PVS1). The variant was not found in gnomAD v2.1.1 (PM2_supporting). It has been detected homozygous in at least 1 proband reported to have Glanzmann thrombasthenia (PM3_supporting; PMID:31029159). In summary, this variant meets the criteria to be classified as pathogenic for autosomal recessive Glanzmann Thrombasthenia based on the ACMG/AMP criteria applied, as specified by the ClinGen PD VCEP: PVS1, PM2_supporting, and PM3_supporting. |