Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Clin |
RCV001290491 | SCV001478529 | uncertain significance | Glanzmann thrombasthenia | 2023-05-16 | reviewed by expert panel | curation | The NM_000419.5:c.1616T>G variant in ITGA2B predicts the missense change, Leu539Arg. The variant is absent from gnomAD v2.1.1 and v3 (PM2_supporting). The variant is reported in an individual homozygous for this variant (PM3_supporting) and the His540Arg in ITGA2B, not meeting criteria for PP4 (PMID: 30792900). The variant also has a moderate REVEL score (0.644) not meeting criteria for PP3 (>0.7) or BP4 (<0.25). In summary, this variant meets the criteria to be classified as uncertain significance for autosomal recessive Glanzmann Thrombasthenia based on the ACMG/AMP criteria applied, as specified by the ClinGen PD VCEP: PM2_Supporting, PM3_supporting (PD VCEP specifications version 2.1). |