Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Clin |
RCV001290493 | SCV001478531 | pathogenic | Glanzmann thrombasthenia | 2020-08-12 | reviewed by expert panel | curation | The NM_000419.5:c.1618del variant in ITGA2B causes a frameshift and premature termination, Gln540SerfsTer25, with nonsense-mediated mRNA decay predicted. The variant is absent in population databases including gnomAD v2.1.1 and v3. The evidence is reported in a homozygous GT patient. Functional evidence from transfection studies in BHK cells show that the variant results in absent integrin expression. In summary, the variant meets criteria to be classified as pathogenic. GT-specific criteria applied: PVS1, PS3, PM2_Supporting, PM3_Supporting. |