Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Clin |
RCV001803411 | SCV002047561 | uncertain significance | Glanzmann thrombasthenia | 2021-11-04 | reviewed by expert panel | curation | The NM_000419.5(ITGA2B):c.1622T>A (p.Leu541Gln) missense variant has been reported at least once, GT19 (PMID: 32237906) displayed mucocutaneous bleeding and impaired aggregation with all agonists except ristocetin, which is highly specific for Glanzmann thrombasthenia (PP4_moderate). Additionally, αIIb surface expression was reduced to 0.371%, as measured by flow cytometry. This variant is absent from gnomAD v2.1.1 (PM2_Supporting). In summary, this variant meets the criteria to be classified as uncertain significance for autosomal recessive Glanzmann Thrombasthenia based on the ACMG/AMP criteria applied, as specified by the ClinGen PD VCEP: PP4_moderate, PM2_supporitng. (VCEP specifications version 2; date of approval 11/04/2021) |