Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Clin |
RCV000852088 | SCV005061687 | uncertain significance | Glanzmann thrombasthenia | 2024-05-02 | reviewed by expert panel | curation | The c.2507G>C variant in ITGA2B is a missense variant predicted to cause substitution of Glycine by Alanine at amino acid 836 (p.Gly836Ala). This variant is absent from gnomAD v4.0.0 (PM2_Supporting). The computational predictor REVEL gives a score of 0.152, which is below the ClinGen PD VCEP threshold of <0.25 and predicts no damaging effect on ITGA2B function (BP4). A male patient is reported homozygous this variant (TGP0413 in PMID: 31064749; PM3_Supporting) however, his phenotype is not detailed enough to apply PP4 as specified by the PD VCEP. Due to conflicting evidence, this variant is classified as a variant of unknown significance for autosomal recessive Glanzmann Thrombasthenia based on the ACMG/AMP criteria applied, as specified by the ClinGen PD-VCEP: PM2_Supporting, PM3_Supporting and BP4 (VCEP specifications version 2). |
NIHR Bioresource Rare Diseases, |
RCV000852088 | SCV000899629 | likely pathogenic | Glanzmann thrombasthenia | 2019-02-01 | criteria provided, single submitter | research |