Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Clin |
RCV001580217 | SCV001809850 | uncertain significance | Glanzmann thrombasthenia | 2024-06-06 | reviewed by expert panel | curation | The NM_000419.5(ITGA2B):c.2570G>T (p.Cys857Phe) missense variant is absent from gnomAD v4.0 (PM2_Supporting). It has been reported in two patients with GT (PMID: 29675921, Patient 439 of the Glanzmann Thrombasthenia Database), both compound heterozygous with variants of uncertain significance. GT39 of PMID: 29675921 meets the criteria for PP4_moderate; including mucocutaneous bleeding, and impaired aggregation with all agonists except ristocetin. There was reduced function of αIIbβ3 measured by flow cytometry, however 43% PAC-1 binding was not considered sufficient to meet PP4_strong. In summary, based on the evidence available at this time, the variant is classified as uncertain significance for GT. GT-specific criteria applied: PM2_supporting and PP4_moderate. |