Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Athena Diagnostics | RCV000518641 | SCV000614305 | likely benign | not specified | 2017-04-17 | criteria provided, single submitter | clinical testing | |
Institute of Human Genetics, |
RCV001253585 | SCV001429377 | uncertain significance | Cerebral arteriopathy, autosomal dominant, with subcortical infarcts and leukoencephalopathy, type 1 | 2024-02-27 | criteria provided, single submitter | clinical testing | Criteria applied: PS4_SUP,PM2_SUP,PP2,PP3 |
Labcorp Genetics |
RCV002527501 | SCV003461969 | uncertain significance | not provided | 2022-02-07 | criteria provided, single submitter | clinical testing | This sequence change replaces aspartic acid, which is acidic and polar, with asparagine, which is neutral and polar, at codon 158 of the NOTCH3 protein (p.Asp158Asn). This variant is present in population databases (rs544773641, gnomAD 0.02%). This missense change has been observed in individual(s) with clinical features of cerebral arteriopathy with subcortical infarcts and leukoencephalopathy (PMID: 30076350). ClinVar contains an entry for this variant (Variation ID: 447851). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is expected to disrupt NOTCH3 protein function. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |