Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
3billion, |
RCV002283754 | SCV002572811 | likely pathogenic | Pendred syndrome | 2022-09-01 | criteria provided, single submitter | clinical testing | The variant is not observed in the gnomAD v2.1.1 dataset. In silico tool predictions suggest damaging effect of the variant on gene or gene product (REVEL: 0.98; 3Cnet: 0.93). Same nucleotide change resulting in same amino acid change has been previously reported to be associated with SLC26A4-related disorder (PMID: 25372295). Different missense changes at the same codon (p.Gly116Asp, p.Gly116Val) have been reported as pathogenic/likely pathogenic with strong evidence (ClinVar ID: VCV001297681 , VCV001346580). Therefore, this variant is classified as Likely pathogenic according to the recommendation of ACMG/AMP guideline. |
Baylor Genetics | RCV004572119 | SCV005056838 | likely pathogenic | Autosomal recessive nonsyndromic hearing loss 4 | 2024-01-27 | criteria provided, single submitter | clinical testing |