Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Women's Health and Genetics/Laboratory Corporation of America, |
RCV004586278 | SCV005077154 | likely pathogenic | Severe combined immunodeficiency disease | 2024-04-19 | criteria provided, single submitter | clinical testing | Variant summary: RAG1 c.2189G>T (p.Cys730Phe) results in a non-conservative amino acid change in the encoded protein sequence. Five of five in-silico tools predict a damaging effect of the variant on protein function. The variant allele was found at a frequency of 8e-06 in 251404 control chromosomes. c.2189G>T has been reported in the literature in at least one compound heterozygous individual affected with Severe Combined Immunodeficiency (e.g. Lee_2014). At least one publication reports experimental evidence evaluating an impact on protein function. The most pronounced variant effect results in null VDJ recombination activity (e.g. Lee_2014). The following publication has been ascertained in the context of this evaluation (PMID: 24290284). No submitters have cited clinical-significance assessments for this variant to ClinVar. Based on the evidence outlined above, the variant was classified as likely pathogenic. |