Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Suna and Inan Kirac Foundation Neurodegeneration Research Laboratory, |
RCV001095392 | SCV001251047 | likely pathogenic | Amyotrophic lateral sclerosis type 1 | 2020-03-31 | criteria provided, single submitter | research | |
Centre for Mendelian Genomics, |
RCV001196130 | SCV001366634 | uncertain significance | Spastic tetraplegia and axial hypotonia, progressive | 2019-06-26 | criteria provided, single submitter | clinical testing | This variant was classified as: Uncertain significance. The available evidence on this variant's pathogenicity is insufficient or conflicting. The following ACMG criteria were applied in classifying this variant: PM2,PP2,PP3. |
Gene |
RCV002291718 | SCV002584265 | uncertain significance | not provided | 2022-10-13 | criteria provided, single submitter | clinical testing | Observed in several unrelated individuals with ALS, but familial segregation information and additional clinical information was not provided (Dangoumau et al., 2014; Tunca et al., 2020); Published functional studies suggest this variant results in formation of aggregates, however additional studies are needed to validate the functional effect of this variant in vivo (Dangoumau et al., 2021); Not observed at significant frequency in large population cohorts (gnomAD); In silico analysis supports that this missense variant has a deleterious effect on protein structure/function; This variant is associated with the following publications: (PMID: 25798606, 28680046, 24611504, 34426522, 33670299, 29709651, 26605782, 33655618, 32579787, 35328090, 23954173) |