Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Invitae | RCV001864977 | SCV002126494 | pathogenic | Peutz-Jeghers syndrome | 2021-07-06 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Pathogenic. Studies have shown that disruption of this splice site results in exon 4 skipping, which introduces a premature termination codon (PMID: 22775437). The resulting mRNA is expected to undergo nonsense-mediated decay. Disruption of this splice site has been observed in individuals with Peutz-Jeghers syndrome (PMID: 16707622, 21118512, 22775437). This variant is not present in population databases (ExAC no frequency). This sequence change affects a donor splice site in intron 4 of the STK11 gene. RNA analysis indicates that this variant induces altered splicing and may result in an absent or disrupted protein product. |