Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Ambry Genetics | RCV000160995 | SCV000278089 | likely pathogenic | Hereditary cancer-predisposing syndrome | 2020-09-18 | criteria provided, single submitter | clinical testing | The p.S240W variant (also known as c.719C>G), located in coding exon 5 of the STK11 gene, results from a C to G substitution at nucleotide position 719. The serine at codon 240 is replaced by tryptophan, an amino acid with highly dissimilar properties. This alteration has been reported in individuals with clinical features of Peutz-Jeghers syndrome (Ngeow J et al. Gastroenterology 2013 Jun; 144(7):1402-9, 1409.e1-5; Zhang Z et al. World J. Gastroenterol. 2020 Apr;26(16):1926-1937; Ambry internal data). This variant was not reported in population-based cohorts in the Genome Aggregation Database (gnomAD). This amino acid position is highly conserved in available vertebrate species. In addition, this alteration is predicted to be deleterious by in silico analysis. Based on the majority of available evidence to date, this variant is likely to be pathogenic. |
Fulgent Genetics, |
RCV000763422 | SCV000894180 | likely pathogenic | Carcinoma of pancreas; Peutz-Jeghers syndrome; Malignant tumor of testis | 2018-10-31 | criteria provided, single submitter | clinical testing | |
Invitae | RCV001041130 | SCV001204728 | likely pathogenic | Peutz-Jeghers syndrome | 2023-03-23 | criteria provided, single submitter | clinical testing | This missense change has been observed in individuals with Peutz-Jeghers syndrome (PMID: 23399955; Invitae). In summary, the currently available evidence indicates that the variant is pathogenic, but additional data are needed to prove that conclusively. Therefore, this variant has been classified as Likely Pathogenic. Algorithms developed to predict the effect of sequence changes on RNA splicing suggest that this variant may create or strengthen a splice site. Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is expected to disrupt STK11 protein function. ClinVar contains an entry for this variant (Variation ID: 182902). This variant is not present in population databases (gnomAD no frequency). This sequence change replaces serine, which is neutral and polar, with tryptophan, which is neutral and slightly polar, at codon 240 of the STK11 protein (p.Ser240Trp). |
Genome- |
RCV001041130 | SCV002057275 | likely pathogenic | Peutz-Jeghers syndrome | 2021-07-15 | criteria provided, single submitter | clinical testing |