Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV000413730 | SCV000490670 | pathogenic | not provided | 2016-04-04 | criteria provided, single submitter | clinical testing | The Y91X nonsense variant in the NR0B1 gene has been reported previously in association withX-linked adrenal hypoplasia congenita (AHC) (Nake et al., 1996; Guo et al., 1996). The Y91X variant was not observed in approximately 6400 individuals of European and African American ancestry in the NHLBI Exome Sequencing Project, indicating it is not a common benign variant in these populations. This variant is predicted to cause loss of normal protein function either through protein truncation or nonsense-mediated mRNA decay. Therefore, we interpret Y91X to be a pathogenic variant. |
OMIM | RCV000011703 | SCV000031935 | pathogenic | Congenital adrenal hypoplasia, X-linked | 1996-10-01 | no assertion criteria provided | literature only | |
Beijing Key Laboratory for Genetic Research of Skeletal Deformity, |
RCV000011703 | SCV001482354 | pathogenic | Congenital adrenal hypoplasia, X-linked | 2019-05-31 | no assertion criteria provided | research |