Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Department of Haematogenetics, |
RCV001526690 | SCV001653522 | pathogenic | Adenylate kinase deficiency | 2021-04-01 | criteria provided, single submitter | clinical testing | A homozygous missense variation in exon 5 of the AK1 gene and one Indian families has chronic nonspherocytic hemolytic anemia (CNSHA) and severe red blood cell (RBC) adenylate kinase (AK) deficiency that results from the amino acid substitution of Lysine for Glutamine at codon 101 (p.Gln101Lys; ENST00000373176.1) was detected. The p.Gln101Lys variant has not been reported in the 1000 genomes, ExAC and our internal databases. The in silico predictions# of the variant are probably damaging by PolyPhen-2 (HumDiv) and damaging by SIFT, LRT and MutationTaster2. The reference codon is conserved across species. In summary, the p.Gln101Lys variant meets our criteria to be classified as pathogenic |
Department of Haematogenetics, |
RCV001506969 | SCV001654247 | pathogenic | Hemolytic anemia due to adenylate kinase deficiency | no assertion criteria provided | research |